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    <TD>Child's Nervous System</TD></TR>
  <TR>
    <TD>=A9&nbsp;Springer-Verlag&nbsp;2006</TD></TR>
  <TR>
    <TD>10.1007/s00381-006-0273-6</TD></TR></TBODY></TABLE><!--Begin =
Abstract-->
<H2 class=3Drubric>Case Report</H2>
<DIV class=3DHeading1><A name=3Dtitle></A>Mixed or metachronous =
germ-cell tumor?=20
</DIV>
<P class=3DAuthorGroup>Kyu-Won&nbsp;Shim<SUP>1</SUP>,=20
Dong-Seok&nbsp;Kim<SUP>1&nbsp;<A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#ContactOfAuthor2"><IMG=20
alt=3D"Contact Information"=20
src=3D"http://www.springerlink.com/content/d11464p17503n454/contact.gif" =

border=3D0></A></SUP> and Joong-Uhn&nbsp;Choi<SUP>1</SUP></P>
<TABLE>
  <TBODY>
  <TR vAlign=3Dtop>
    <TD><SPAN class=3DAffiliation><A =
name=3DAff1></A>(1)&nbsp;</SPAN></TD>
    <TD><SPAN class=3DAffiliation>Department of Neurosurgery, Brain =
Korea 21=20
      Project for Medical Science, Brain Research Institute, Yonsei =
University=20
      College of Medicine, Seoul, South =
Korea</SPAN></TD></TR></TBODY></TABLE>
<P><A name=3DContactOfAuthor2></A></P>
<TABLE class=3DContact>
  <TBODY>
  <TR>
    <TD vAlign=3Dtop><IMG alt=3D"Contact Information"=20
      =
src=3D"http://www.springerlink.com/content/d11464p17503n454/contact.gif" =

      border=3D0></TD>
    =
<TD><STRONG>Dong-Seok&nbsp;</STRONG><STRONG>Kim</STRONG><STRONG></STRONG>=
<BR><STRONG>Email:=20
      </STRONG><A=20
      =
href=3D"mailto:dskim33@yumc.yonsei.ac.kr">dskim33@yumc.yonsei.ac.kr</A></=
TD></TR></TBODY></TABLE>
<P class=3DAffiliation><STRONG>Received:=20
</STRONG>28&nbsp;November&nbsp;2005&nbsp;&nbsp;<STRONG>Revised:=20
</STRONG>21&nbsp;June&nbsp;2006&nbsp;&nbsp;<STRONG>Published online:=20
</STRONG>23&nbsp;December&nbsp;2006 </P>
<DIV class=3DAbstract><A name=3DAbs1></A><SPAN =
class=3DAbstractHeading>Abstract</SPAN>
<DIV class=3DAbstractSection>
<DIV class=3D""><SPAN class=3DAbstractSectionHeading><A =
name=3DASec1></A>Objective and=20
importance&nbsp;&nbsp;</SPAN>We report the extremely rare occurrence of =
a second=20
germ-cell tumor at a different site and with different histological =
types long=20
after total resolution of a pineal germinoma. </DIV></DIV>
<DIV class=3DAbstractSection>
<DIV class=3D""><SPAN class=3DAbstractSectionHeading><A =
name=3DASec2></A>Clinical=20
presentation&nbsp;&nbsp;</SPAN>A 21-year-old man who presented with =
headache and=20
diplopia was admitted to our hospital. Neuroradiological studies =
revealed a=20
tumor in the pineal region. The tumor was biopsied with endoscope, and =
third=20
ventriculostomy was performed. Histologically, the tumor proved to be a=20
germinoma. The patient received 3&nbsp;cycles of combination =
chemotherapy=20
consisting of carboplatin and etoposide with radiotherapy. The tumor was =
totally=20
resolute. Twelve months later, he was readmitted with headache and =
diplopia.=20
Neuroradiological studies showed a tumor in the right temporal lobe.=20
</DIV></DIV>
<DIV class=3DAbstractSection>
<DIV class=3D""><SPAN class=3DAbstractSectionHeading><A=20
name=3DASec3></A>Intervention&nbsp;&nbsp;</SPAN>The second tumor was =
totally=20
removed. Histologically, the tumor proved to be a mixed germ-cell tumor, =
which=20
consisted a yolk-sac tumor and a germinoma. After the second course of=20
chemotherapy, magnetic resonance image studies revealed no evidence of =
the=20
tumor. </DIV></DIV>
<DIV class=3DAbstractSection>
<DIV class=3D""><SPAN class=3DAbstractSectionHeading><A=20
name=3DASec4></A>Conclusion&nbsp;&nbsp;</SPAN>The second tumor was =
considered to=20
be a metachronous neoplasm rather than a recurrence of the original =
mixed=20
germ-cell tumor, which consisted a yolk-sac tumor and a germinoma.=20
</DIV></DIV></DIV>
<P class=3DKeyword><SPAN =
class=3DKeywordHeading>Keywords&nbsp;&nbsp;</SPAN>Germ-cell=20
tumor&nbsp;-&nbsp;Metachronous&nbsp;-&nbsp;Germinoma&nbsp;-&nbsp;Mixed =
germ-cell=20
tumor </P>
<DIV class=3D""><A name=3DSec1></A>
<HR>

<DIV class=3Dheading2>Introduction</DIV>
<P class=3D"">Germ-cell tumors in the central nervous system usually =
arise in the=20
midline of the brain. They are commonly seen in the pineal region, the=20
suprasellar cistern, the basal ganglia, and the thalamus. Intracranial =
germ-cell=20
tumors are classified histologically into teratoma, germinoma, embryonal =

carcinoma, endodermal sinus tumors, and choriocarcinoma and their mixed =
types.=20
Pineal region tumors are uncommon, comprising 3=9611% of all childhood =
tumors=20
[<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR1">1</A></CITE>,=20
<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR2">2</A></CITE>]=20
with a somewhat higher incidence in Asian races. Most brain tumors in =
the pineal=20
region are intracranial germ-cell tumors, especially germinoma [<CITE><A =

href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR3">3</A></CITE>].=20
The ratio of their incidence in men to their incidence in women is 7 to =
3. It is=20
common for man to have intracranial germ-cell tumors in the pineal =
region. The=20
incidence of germ-cell tumors originating simultaneously from the pineal =
and=20
suprasellar regions was reported to be 12.8% [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR4">4</A></CITE>]=20
and 5.9% [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR3">3</A></CITE>].=20
The curability of these tumors depends on the histology. Germinomas can =
be cured=20
by radiotherapy and/or chemotherapy. The 5-year survival rate of =
patients with=20
germinomas treated with radiotherapy is more than 90% [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR5">5</A></CITE>=96<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR9">9</A></CITE>].=20
Pure germinomas are considered to have a good prognosis and a low =
recurrence=20
rate after total resolution. It is rare for a second germ-cell tumor to =
occur at=20
a different site and with different histological types after total =
resolution of=20
a pure pineal germinoma [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR10">10</A></CITE>].=20
In the case of the mature teratomas, which were totally removed =
surgically,=20
radiation therapy does not perform usually. Therefore, recurrence and =
distant=20
metastasis of mature teratoma were reported not uncommonly. However, =
because=20
pure germinomas usually received radiation therapy, the recurrence and =
distant=20
metastasis are very rare. In addition, the metachronous, mixed germ-cell =
tumor=20
after total resolution of germinoma, which received chemotherapy and =
radiation=20
therapy, is very unusual and extremely rare. In the literature, the =
metachronous=20
germ-cell tumors are mostly from mature teratomas, but our case is mixed =

germ-cell tumor from the germinoma, which consisted a yolk-sac tumor and =
a=20
germinoma. The first tumor, germinoma, was diagnosed with endoscopic =
biopsy.=20
Thus, underestimation of mixed component was possible. However, serum =
and=20
cerebrospinal fluid marker studies are compatible with germinoma. =
Moreover, the=20
response to the additional treatment suggested the pure germinoma. =
Because the=20
location of the second tumor was parenchyma of the right temporal lobe, =
not the=20
temporal horn of the ventricle, the possibility of the ventricular =
seeding was=20
very low. </P>
<P class=3D"">There was a report of recurrence as a yolk-sac tumor in =
the=20
peritoneal cavity through the ventriculoperitoneal shunt. The patient =
was=20
initially diagnosed with germinoma and received chemotherapy and =
radiation=20
therapy. The tumor totally disappeared after the treatment, but =
13&nbsp;months=20
later, intraperitoneal tumor was detected. The tumor was eradicated with =
a=20
combination of systemic chemotherapy and local irradiation, with no =
residual=20
viable tumor cells confirmed at final surgical extirpation [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR11">11</A></CITE>].=20
The direct seeding through the shunt system was possible. </P>
<P class=3D"">This may be the first case report about the intracranial,=20
metachronous, mixed germ-cell tumor which is from the totally resolute=20
germinoma. </P></DIV>
<DIV class=3D""><A name=3DSec2></A>
<HR>

<DIV class=3Dheading2>Case presentation</DIV>
<DIV class=3D""><A name=3DSec3></A>
<DIV class=3DHeading3>The first admission</DIV>
<DIV class=3DPara>
<DIV class=3D"">In September 2003, a 21-yr-old man was admitted with =
headache and=20
diplopia. On admission, he was lethargic and showed a mild degree of =
medial gaze=20
paresis of left eyeball. No other abnormal neurological deficits were =
noted.=20
Results of hormonal tumor marker studies including alpha-fetoprotein =
(&#945;-FP) and=20
beta-human chorionic gonadotropin (&#946;-hCG) were in normal ranges. =
Magnetic=20
resonance image (MRI) showed strongly enhancing mass lesion in the =
pineal region=20
accompanied by moderate obstructive hydrocephalus (Fig.&nbsp;<A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#Fig1">1</A>a,b).=20
No abnormality was found on his spinal MRI. To obtain the tumor tissue =
for=20
diagnosis and relieve the hydrocephalic symptom, an endoscopic surgery =
was=20
performed. Through the right Kocher=92s point, the tumor was removed =
partially=20
with endoscope. A gross morphology of the tumor via endoscopic view was =
a=20
germinoma. The endoscopic third ventriculostomy was performed to relieve =
the=20
hydrocephalic symptom. Surgical specimen proved to be a germinoma, which =
was=20
composed of large polygonal cells with large, round, and vesicular =
nuclei and=20
sheath-like arrangement. No malignant features were observed within the =
prepared=20
specimen (Fig.&nbsp;<A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#Fig2">2</A>).=20
The patient received 3&nbsp;cycles of combination chemotherapy =
consisting of=20
carboplatin and etoposide. And then, he received 30.6&nbsp;Gy of =
localized=20
irradiation on pineal gland for 5&nbsp;weeks. The tumor was totally =
resolute=20
(Fig.&nbsp;<A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#Fig3">3</A>a,b).=20
And then, he was followed in the outpatient clinic. One month after the=20
completion of adjuvant therapy, the patient suffered from headache and =
diplopia.=20
Brain computed tomography with contrast enhancement was taken. There was =
no=20
abnormal finding except for the minimal contrast enhancement on the =
pineal=20
region, which was not considered as tumorous condition. At 3&nbsp;months =
after=20
the completion of adjuvant therapy, the condition of the patient was =
good, and=20
the hormone was within the normal range. Therefore, we considered the =
patient to=20
have a complete resolution. We tried to see him 6&nbsp;months later and =
to take=20
brain MRI, but the patient did not appear.=20
<DIV class=3DFigure><A name=3DFig1></A><IMG=20
alt=3DMediaObjects/381_2006_273_Fig1_HTML.jpg=20
src=3D"http://www.springerlink.com/content/d11464p17503n454/MediaObjects/=
381_2006_273_Fig1_HTML.jpg"></DIV>
<DIV class=3DCapt><SPAN =
class=3DCaptNr>Fig.&nbsp;1&nbsp;</SPAN>Pretreatment=20
gadolinium-enhanced axial (<B>a</B>) and sagittal (<B>b</B>) T1-weighted =
MR=20
images show strongly enhancing intraventricular mass in the pineal =
region with=20
moderate ventriculomegaly </DIV>
<HR>

<DIV class=3DFigure><A name=3DFig2></A><IMG=20
alt=3DMediaObjects/381_2006_273_Fig2_HTML.jpg=20
src=3D"http://www.springerlink.com/content/d11464p17503n454/MediaObjects/=
381_2006_273_Fig2_HTML.jpg"></DIV>
<DIV class=3DCapt><SPAN class=3DCaptNr>Fig.&nbsp;2&nbsp;</SPAN>The =
tissue of pineal=20
region tumor was taken with endoscope. The prepared specimen showed pure =

germinoma. <B>a</B> Relatively uniform-sized large polygonal cells =
arranged=20
something like a sheet. <B>b</B> In high-power magnification view, large =

polygonal cell with large, round, and vesicular nuclei and abundant =
cytoplasm=20
</DIV>
<HR>

<DIV class=3DFigure><A name=3DFig3></A><IMG=20
alt=3DMediaObjects/381_2006_273_Fig3_HTML.jpg=20
src=3D"http://www.springerlink.com/content/d11464p17503n454/MediaObjects/=
381_2006_273_Fig3_HTML.jpg"></DIV>
<DIV class=3DCapt><SPAN class=3DCaptNr>Fig.&nbsp;3&nbsp;</SPAN>The =
follow-up MRI=20
after 3&nbsp;cycles of chemotherapy and radiation showed total =
resolution of=20
pineal region tumor </DIV>
<HR>
</DIV></DIV></DIV>
<DIV class=3D""><A name=3DSec4></A>
<DIV class=3DHeading3>The second admission</DIV>
<P class=3D"">He was readmitted in March 2005 for aggravation of =
headache and=20
diplopia.</P>
<DIV class=3DPara>
<DIV class=3D"">Gadolinium-enhanced MR images depicted a homogeneously =
enhanced,=20
2.8=D72.8-cm-sized, round-shaped mass at the right temporal lobe =
(Fig.&nbsp;<A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#Fig4">4</A>).=20
Results of hormonal tumor marker studies, including &#945;-FP and =
&#946;-hCG, were=20
21,468.66&nbsp;IU/ml (NL 0&#8201;&#8764;&#8201;7&nbsp;IU/ml) and =
&lt;2.0&nbsp;IU/ml (NL=20
0&#8201;&#8764;&#8201;10&nbsp;IU/ml), respectively. On April 4, 2005, =
the tumor was totally=20
resected via transcortical, transinferior temporal gyrus approach. The =
tumor=20
consisted of a solid portion, and total extirpation of the tumor was =
done=20
easily. Histopathologic examination confirmed a diagnosis of a mixed =
germ-cell=20
tumor containing the component of a yolk-sac tumor and a germinoma.=20
Sh=FBller=96Duval bodies, the typical finding of the yolk-sac tumor, =
were noted=20
(Fig.&nbsp;<A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#Fig5">5</A>a).=20
The immunohistochemical staining of the tumor was performed to confirm =
the=20
diagnosis. Placenta alkaline phosphatase and &#945;-fetoprotein were all =
positive on=20
certain area of the tumor specimen. The main component of the tumor was =
the=20
yolk-sac tumor, whose area was well stained with &#945;-fetoprotein =
(Fig.&nbsp;<A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#Fig5">5</A>c).=20
The placenta alkaline phosphatase stained relatively small area at the =
periphery=20
of the yolk-sac tumor component (Fig.&nbsp;<A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#Fig5">5</A>b).=20
Postoperative days were uneventful. The follow-up MRI was performed, and =
there=20
was no evidence of residual tumor. Further postoperative adjuvant =
therapy was=20
planned. Eventually, he was discharged without any neurological =
deficits. He=20
received the 4&nbsp;cycles of high-dose adjuvant chemotherapy with =
peripheral=20
blood stem-cell transplantation. During the course, the level of serum =
&#945;-FP was=20
gradually decreased. The &#945;-FP was 353.07&nbsp;IU/ml at 1&nbsp;month =
after the=20
second operation. After the second course of high-dose chemotherapy, the =
&#945;-FP=20
was 6.72&nbsp;IU/ml. After the completion of 4&nbsp;cycles of high-dose=20
chemotherapy and peripheral blood stem-cell transplantation, the serum =
&#945;-FP was=20
within the normal range. At that time, the brain MRI was performed, and =
there=20
was no evidence of recurrence. After that, the patient was followed at =
the=20
outpatient department. The patient was doing well, and the &#945;-FP was =
within the=20
normal range which was taken in 3&nbsp;months interval. The brain MRI =
was=20
performed 1&nbsp;year after the second operation, and there was no =
evidence of=20
recurrence.=20
<DIV class=3DFigure><A name=3DFig4></A><IMG=20
alt=3DMediaObjects/381_2006_273_Fig4_HTML.jpg=20
src=3D"http://www.springerlink.com/content/d11464p17503n454/MediaObjects/=
381_2006_273_Fig4_HTML.jpg"></DIV>
<DIV class=3DCapt><SPAN =
class=3DCaptNr>Fig.&nbsp;4&nbsp;</SPAN>Gadolinium-enhanced=20
T1-weighted axial (<B>a</B>) and coronal (<B>b</B>) MR images showed=20
homogeneously enhancing oval-shaped mass at the right temporal lobe =
</DIV>
<HR>

<DIV class=3DFigure><A name=3DFig5></A><IMG=20
alt=3DMediaObjects/381_2006_273_Fig5_HTML.jpg=20
src=3D"http://www.springerlink.com/content/d11464p17503n454/MediaObjects/=
381_2006_273_Fig5_HTML.jpg"></DIV>
<DIV class=3DCapt><SPAN class=3DCaptNr>Fig.&nbsp;5&nbsp;</SPAN>The =
surgical specimen=20
was composed of two components. The specimen was composed mainly of a =
yolk-sac=20
tumor area (<B>a</B>), which contained the typical finding of yolk-sac =
tumor,=20
Sh=FBller=96Duval bodies. The small area of germinoma was found at the =
periphery of=20
the yolk-sac tumor component. The area of the yolk-sac tumor was stained =
with=20
&#945;-fetoprotein (<B>c</B>) and the germinoma area with placenta =
alkaline=20
phosphatase (<B>b</B>) </DIV>
<HR>
</DIV></DIV></DIV></DIV>
<DIV class=3D""><A name=3DSec5></A>
<HR>

<DIV class=3Dheading2>Discussion</DIV>
<P class=3D"">Based on histology, intracranial germ-cell tumors are =
largely=20
classified into germinomas, nongerminomatous germ-cell tumors (teratoma, =

embryonal carcinoma, endodermal sinus tumor, and choriocarcinoma), and =
mixed=20
germ-cell tumors [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR12">12</A></CITE>,=20
<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR13">13</A></CITE>].=20
The most common subtype is germinoma consisting of 50% or more in Far =
Eastern=20
Asian countries and 41% in Western countries. Each subtype of =
nongerminomatous=20
germ-cell tumors is less common and frequently occurs as a component of =
mixed=20
germ-cell tumors, which accounts for 10=9630% of all germ-cell tumors. =
Teratoma is=20
next to germinoma, accounting for about 15=9620% and yolk-sac tumor, and =

choriocarcinoma is the least common, comprising less than 5% [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR7">7</A></CITE>,=20
<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR14">14</A></CITE>].=20
Mixed germ-cell tumors are composed of at least two different germ-cell=20
elements, of which at least one is primitive. The most common =
association is=20
germinoma and mature teratoma, which has been estimated to occur in =
one-fifth of=20
all reported cases. Other mixtures of germinoma and yolk-sac tumor, =
immature or=20
mature teratoma with embryonal carcinoma, and/or choriocarcinoma may =
also be=20
present. However, mixture of germinoma and choriocarcinoma is extremely =
rare=20
[<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR7">7</A></CITE>].=20
Our mixture of germinoma and yolk-sac tumor is relatively not common. =
Moreover,=20
the tumor was metachronous. </P>
<P class=3D"">The age distribution of intracranial teratomas showed a =
peak=20
incidence during the first two decades of life and mostly in children =
[<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR15">15</A></CITE>,=20
<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR16">16</A></CITE>],=20
whereas for germinoma, it was in the early pubertal years. Jennings et =
al.=20
[<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR14">14</A></CITE>]=20
postulated that the neuroendocrine events of puberty might be a =
=93triggering=94=20
effect on the abrupt rise of germ-cell tumors in the puberty. The =
author=92s case=20
was a 21-year-old man. Thus, the neuroendocrinological triggering effect =
on its=20
recurrence was not very likely. </P>
<P class=3D"">Initial presentation of our case was germinoma. The tumor =
markers=20
were all negative on both cerebrospinal fluid and serum. The tumor was=20
completely resolute after chemotherapy and radiotherapy. Thereafter, the =
tumor=20
recurred in the distant region, temporal lobe. The location of the tumor =
in the=20
temporal lobe was outside of the radiation field, not either in the =
trajectory=20
of endoscope or cerebrospinal fluid pathway. Therefore, the tumor =
recurred from=20
neither the cerebrospinal fluid nor the surgical inoculation. Ono et al. =

[<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR17">17</A></CITE>]=20
described the four patterns of recurrence with respect to mechanism and=20
appropriate treatment. Type-I germinoma recurrence, characterized by=20
intracranial recurrence caused by an inadequate initial irradiation =
field, was=20
treated by total craniospinal irradiation. Type-II recurrence, =
characterized by=20
a benign teratoma caused by late growth of the teratoma component, was =
treated=20
by surgery alone. All patients with these patterns of recurrence are =
still=20
alive. Type-III local recurrence is characterized by human chorionic=20
gonadotropin- or &#945;-fetoprotein-producing tumors of extraembryonic =
origin. This=20
pattern of recurrence should be treated by chemotherapy or radiosurgery. =
Type-IV=20
germinoma recurrence consists of extraneural metastasis without evidence =
of=20
intracranial recurrence. According to his classification, our case was =
not=20
included in any of the subtypes. </P>
<P class=3D"">In the literature, the relationship between serum tumor =
marker level=20
and histological appearance has been studied, and it suggested the =
following=20
conclusions. First, macroscopically total removal of the germ-cell tumor =
does=20
not mean complete cure. Second, the measurement of serum tumor markers, =
such as=20
human chorionic gonadotropin and &#945;-fetoprotein, does not always =
detect=20
recurrence of the tumor. Radiotherapy may be required to prevent the =
recurrence=20
of a tumor marker-producing germ-cell tumor even though histological =
examination=20
does not detect immature cells in the surgically removed tissue =
[<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR18">18</A></CITE>].=20
Macroscopically total removal of a germ-cell tumor does not signify=20
cytologically complete removal of the tumor. The surgically removed =
tissue does=20
not reveal all the characteristics of a germ-cell tumor. The occurrence =
of the=20
mixed type of mature teratoma, germinoma, and malignant germ-cell tumor, =
such as=20
choriocarcinoma or endodermal sinus tumor, is an evidence of this. A =
recurrence=20
long after the initial treatment is also quite common. The fate of an=20
intracranial germ-cell tumor cannot be predicted simply by the =
morphological=20
appearance of a piece of tumor that has been surgically removed. =
Complete=20
clinical remission is defined as normalization of the tumor markers and =
the=20
absence of residual tumor. Initial follow-up examination after =
completion of=20
chemotherapy must be performed in short intervals, including frequent =
evaluation=20
of the tumor marker. Nevertheless, we could not perform either follow-up =
MRI at=20
6&nbsp;months after completion of treatment nor tumor marker due to =
follow-up=20
loss for several months. </P>
<P class=3D"">Sugimoto et al. [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR10">10</A></CITE>]=20
reported six cases of distant recurrence of mature teratoma as mixed =
germ-cell=20
tumor. The primary sites were the third ventricle and the adjacent =
structure.=20
The sites of recurrences were the adjacent structures of the third =
ventricle.=20
The histopathologic findings of the recurring tumor were four =
germinomas, one=20
mature teratoma, and one embryonal carcinoma. His recurring cases were =
all=20
located around the third ventricle. In his cases, the second tumors, =
which=20
occurred in the same location with the primary tumor, were most =
plausibly=20
considered as a recurrence from a microscopic residue of germinoma =
component in=20
previously resected mature teratoma despite the long silent period. =
Other=20
possibilities include the sporadic acceleration of a localized =
hamartomatous=20
and/or dysplastic process of preexisting germ cells. </P>
<P class=3D"">Some pathogeneses have been postulated on the development =
of=20
metachronous germ-cell tumors. Firstly, although the recurrence of=20
nongerminomatous germ-cell tumor usually occurs within 1&nbsp;year after =

treatment [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR19">19</A></CITE>],=20
there is a good possibility of tumor recurrence or dissemination =
especially in=20
the mixed tumors that are composed of various combinations of two or =
more types=20
of germ-cell tumors. Secondly, although it is uncertain whether the =
antecedent=20
presence of germ cells is due to germinal aberrant migration of germ =
cells,=20
embryonic =93cell rest=94, or localized hamartomatous or dysplastic =
processes=20
[<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR20">20</A></CITE>],=20
the preexisting germ cells have been implicated. Thirdly, it may develop =
due to=20
genetic alterations that lead to mutational inactivation of tumor =
suppressor=20
genes or activation of oncogenes [<CITE><A=20
href=3D"http://www.springerlink.com/content/d11464p17503n454/fulltext.htm=
l#CR21">21</A></CITE>].=20
</P>
<P class=3D"">The germ-cell tumor is originated from the totipotent germ =
cell. The=20
germ cell can be found anywhere in the whole human body, especially in =
the=20
midline structure. Initial follow-up examination after completion of=20
chemotherapy must be performed in short intervals, including frequent =
evaluation=20
of the tumor marker. Treatment response is evaluated by follow-up MRI =
scans=20
every 6&nbsp;months until the third year after diagnosis and then at =
1-year=20
interval. We must observe the rules because the germ cell is totipotent. =

</P></DIV>
<DIV class=3D""><A name=3DSec6></A>
<HR>

<DIV class=3Dheading2>Conclusion</DIV>
<P class=3D"">The second tumor was considered to be a de novo =
metachronous=20
neoplasm rather than a recurrence of the original mixed germ-cell tumor =
that=20
consisted a yolk-sac tumor and a germinoma. The location of the second =
tumor was=20
in temporal lobe, which was not in the axis of the ventricular system. =
We think=20
that if primordial germ-cell groups exist along the midline of the =
brain, more=20
than two primordial germ cell-groups could give rise to metachronous =
neoplasms=20
at different sites and with different histological types. Because the =
germ-cell=20
tumor was totipotent itself, even if the tumor was totally resolute, =
thorough=20
and close follow-up should be needed. </P></DIV>
<P></P>
<HR>

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    <TD>&nbsp;</TD></TR></TBODY></TABLE></BODY></HTML>

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